eprintid: 1452376
rev_number: 46
eprint_status: archive
userid: 608
dir: disk0/01/45/23/76
datestamp: 2014-10-22 18:56:34
lastmod: 2021-12-11 23:44:17
status_changed: 2014-10-22 18:56:34
type: article
metadata_visibility: show
item_issues_count: 0
creators_name: Wedatilake, Y
creators_name: Plagnol, V
creators_name: Anderson, G
creators_name: Paine, SM
creators_name: Clayton, PT
creators_name: Jacques, TS
creators_name: Rahman, S
title: Tubular aggregates caused by serine active site containing 1 (SERAC1) mutations in a patient with a mitochondrial encephalopathy.
ispublished: pub
divisions: UCL
divisions: B02
divisions: C08
divisions: D09
divisions: F99
divisions: D13
divisions: G22
divisions: G23
note: © 2014 The Authors. Neuropathology and Applied Neurobiology published by John Wiley & Sons Ltd . on behalf of British Neuropathological Society.
This is an open access article under the terms of the Creative Commons Attribution License, which permits use, distribution and reproduction in any medium, provided the original work is properly cited.
abstract: Tubular aggregates (TAs) are cytoplasmic aggregates of membranous tubules derived from the sarcoplasmic reticulum and usually 50–70 nm in diameter [1]. They may be seen in a range of genetic myopathies, including gyrate atrophy caused by ornithine aminotransferase deficiency, periodic paralysis and two disorders of glycosylation caused by mutations in the GFPT1 and DPAGT1 genes [2,3]. In addition, they may occur as a minor or inconsistent feature in a wide range of myopathies or be the predominant feature in idiopathic or congenital myopathies [4]. However, the mechanisms underlying TA formation remain poorly understood. We now report the development of TAs in a patient with a lipid remodelling disorder, providing new insight into the formation of TAs.
date: 2015-04
official_url: http://dx.doi.org/10.1111/nan.12190
vfaculties: VFLS
oa_status: green
full_text_type: pub
language: eng
primo: open
primo_central: open_green
article_type_text: Journal Article
verified: verified_manual
elements_source: PubMed
elements_id: 987032
doi: 10.1111/nan.12190
lyricists_name: Clayton, Peter
lyricists_name: Jacques, Thomas
lyricists_name: Plagnol, Vincent
lyricists_name: Rahman, Shamima
lyricists_id: PTCLA52
lyricists_id: TJACQ32
lyricists_id: VYPLA47
lyricists_id: SRAHM75
full_text_status: public
publication: Neuropathol Appl Neurobiol
volume: 41
number: 3
pagerange: 399 - 402
event_location: England
citation:        Wedatilake, Y;    Plagnol, V;    Anderson, G;    Paine, SM;    Clayton, PT;    Jacques, TS;    Rahman, S;      (2015)    Tubular aggregates caused by serine active site containing 1 (SERAC1) mutations in a patient with a mitochondrial encephalopathy.                   Neuropathol Appl Neurobiol , 41  (3)   399 - 402.    10.1111/nan.12190 <https://doi.org/10.1111/nan.12190>.       Green open access   
 
document_url: https://discovery-pp.ucl.ac.uk/id/eprint/1452376/1/nan12190.pdf